Ameloblastomas are locally aggressive gnathic tumors with a high propensity for recurrence. Presentation of an ameloblastoma exclusively in the sinonasal tract is extremely rare, with few reported cases in the literature. Management involves surgical excision and close follow-up. We report a case in which the patient had complete unilateral nasal obstruction caused by an ameloblastoma. The tumor was completely excised endoscopically, and at the 12-month follow-up, there was no evidence of recurrence.